ABSTRACT
Aims: An Odontoma is usually found in the surrounding area of the unerupted permanent tooth bud and rarely adjacent to the primary central incisor. Histopathological examination of the Odontoma revealed presence of surface invagination similar to Dens invaginatus. Presentation of Case: A seven year-old healthy girl presented with an unerupted maxillary left primary central incisor along with swelling of labial gingiva in that region. No history of traumatic injury was recorded. Radiological examination revealed impacted primary maxillary left central incisor and three irregular masses of calcified tooth like tissues. Discussion: Odontomas are commonly occuring hamartomas associated with permanent dentition. Odontomas are rarely associated with Primary dentition. Multiple Odontomas leading to impaction of primary incisors is still rarer. This report presents a case of an impacted primary central incisor and unerupted permanent central incisor due to multiple odontomas, one of which was histologically diagnosed as multiple compound odontoma with Dens invaginatus. The Odontomas and impacted primary central were surgically removed to facilitate the eruption of permanent incisor. Conclusion: This report presents a unique and rare case of multiple Odontomas leading to impaction of primary tooth and unerupted permanent incisor. This report also proves Odontomas with deep surface invagination similar to Dens Invaginatus can be present.