ABSTRACT
PURPOSE: To describe a case of severe bilateral visual loss in a patient with olfactory groove meningioma. CASE SUMMARY: A 64-year-old man presented with a 1-year history of anosmia, progressive loss of vision and visual field deficit. Presenting visual acuity was Counting fingers at 10 cm, and visual field exam showed total visual field defect in both eyes, but there was no remarkable finding to warrant an ophthalmologic examination except mild nucleosclerosis in both eyes and temporal pallor in the left optic nerve head. A brain MRI scan was performed and revealed an olfactory groove meningioma. Surgical resection was performed, and pathologic findings showed meningotheliomatous meningioma. Two months later, the patient was healthy, but no significant improvement of visual acuity or visual field was observed. CONCLUSIONS: In patients with unexplained visual loss with anosmia, olfactory groove meningioma should be considered.