RESUMEN
La rinosporidiosis es una enfermedad granulomatosa rara producida por el microorganismo Rhinosporidium seeberi. A pesar de ser considerada una infección endémica en algunas zonas de Asia, en nuestro país es una enfermedad extremadamente rara. Se presenta el caso clínico de un escolar de 10 años que consulta por aumento de volumen en fosa nasal izquierda de 1 mes de evolución, de crecimiento progresivo, con epistaxis autolimitada, presentando al examen físico una lesión polipoídea, en la cual, no existiendo sospecha previa, se determinó mediante histopatología la presencia de rinosporidio-sis. Se discute la epidemiología de la enfermedad, sus mecanismos de diseminación, alternativas de tratamiento y principales complicaciones.
Rhinosporidiosis is a rare granulomatous disease produced by the microorganism Rhinosporidium seeberi. Despite being considered an endemic infection in some areas of Asia, in our country it is an extremely rare disease. We present the case of a 10 year-old boy who consult for increased volumen in the left nostril of 1 month evolution, with progressive growth, self-limited epistaxis, and a physical examination with a polypoid lesion, in which there were no prior suspicion, histopathology determined the presence of rhinosporidiosis. Epidemiology of the disease, its dissemination mechanisms, treatment options and major complications are discussed.
Asunto(s)
Humanos , Masculino , Niño , Rinosporidiosis/diagnóstico , Rinosporidiosis/cirugía , Rinosporidiosis/patología , Rhinosporidium/aislamiento & purificaciónRESUMEN
Rhinosporidiosis is a chronic granulomatous infection caused by Rhinosporidium seeberi. Rhinosporidiosis has been reported from many countries but is endemic in certain parts of India and Sri Lanka. The common sites of involvement are the nose and nasopharynx followed by ocular tissue. Rhinosporidiosis is also known to involve many rare sites and may become disseminated to occur in a generalized form. Rhinosporidiosis of the parotid duct is rare and only five reported cases could be found in the literature. We report three cases of rhinosporidiosis of parotid duct presenting clinically as a parotid duct cyst. Rhinosporidiosis was diagnosed by histopathology. None of these patients had rhinosporidiosis at any other site
Asunto(s)
Adulto , Animales , Quistes/patología , Femenino , Histocitoquímica , Humanos , India , Masculino , Persona de Mediana Edad , Glándula Parótida/patología , Rinosporidiosis/diagnóstico , Rhinosporidium/aislamiento & purificación , Conductos Salivales/patología , Sri LankaRESUMEN
Rhinosporidiosis is a benign chronic granulomatous infection caused by Rhinosporidium seeberi. Rhinosporidiosis is endemic in south Asia, notably in southern India and Sri Lanka. Majority of the cases have been reported to occur in upper respiratory sites, notably anterior nares, nasal cavity, nasopharynx, larynx and soft palate. Only two rare cases of involvement of parotid duct, have been reported in literature. Hence, this case will probably be the third to be reported.
Asunto(s)
Anciano , Animales , Humanos , Masculino , Enfermedades de las Parótidas/diagnóstico , Enfermedades de las Parótidas/parasitología , Enfermedades de las Parótidas/cirugía , Glándula Parótida/parasitología , Glándula Parótida/patología , Glándula Parótida/cirugía , Rinosporidiosis/diagnóstico , Rinosporidiosis/cirugía , Rhinosporidium/aislamiento & purificación , Rhinosporidium/patogenicidad , Conductos Salivales/parasitología , Conductos Salivales/patología , Conductos Salivales/cirugíaRESUMEN
We report the case of a young Chhattisgarhi male with polymorphic dermosporidiosis (cutaneous rhinosporidiosis). He had multiple subcutaneous nodules and an ecthymatoid skin lesion along with nasal rhinosporidiosis. The diagnosis was confirmed by demonstration of sporangia with endospores in fine-needle aspiration cytology (FNAC), histopathology, and imprint smear from the skin lesions. Treatment was by surgical excision, electrocoagulation, and dapsone. There was no recurrence. Dermatologists should be aware of the diverse cutaneous manifestations of this primarily nasal disease. This is the second published report of polymorphic dermosporidiosis, and the first one reporting an ecthymatoid lesion.
Asunto(s)
Adulto , Animales , Humanos , Pierna/patología , Masculino , Enfermedades Nasales/parasitología , Rinosporidiosis/patología , Rhinosporidium/aislamiento & purificación , Piel/patología , Enfermedades Cutáneas Parasitarias/patología , Úlcera/parasitologíaRESUMEN
Rhinosporidiosis is a chronic recurrent infective granulomatous disease of man and animals. It is endemic in India and Sri Lanka. Rhinosporidiosis is a chronic disease commonly involving the nose and nasopharynx. Cutaneous lesions, although rare, can occur due to autoinoculation or due to hematogenous spread. However, disseminated cutaneous lesions presenting as tumor-like swellings are rare. We report here a 48-year-old immunocompetent patient who had disseminated painless cutaneous tumor-like swellings over both the upper limbs, abdomen, left buttock and calf since 10 months, gradually increasing in size. On inquiring, the patient gave history of excisions and electrocauterization of subglottic and nasal polyps. Histopathological examination of these lesions was suggestive of rhinosporidiosis. The general and systemic examinations of the patient did not reveal any abnormality.
Asunto(s)
Animales , Codo/parasitología , Humanos , Hipofaringe/parasitología , Inmunocompetencia , Masculino , Persona de Mediana Edad , Rinosporidiosis/patología , Rhinosporidium/aislamiento & purificación , Enfermedades Cutáneas Parasitarias/parasitología , Tejido Subcutáneo/parasitología , Tomografía Computarizada por Rayos XRESUMEN
The authors present a case series of 54 subjects of Rhinosporidium. They were reported in two years at a tertiary care hospital of Western Orissa. The clinically diagnosed cases by ophthalmologists were confirmed by histopathological samples following surgery. In our series, we noted Rhinosporidium seeberi organisms as the main causative agent. Males were affected three times more than females. Children less than 10 years of age comprised more than 50% of our series. In 91% of cases, the conjunctiva was the site of this infection. Total excision of fungal mass was carried out in all cases and two cases had recurrence between 9 and 12 months following intervention. Although this is an endemic area for such infestation, unilateral manifestation observed in all cases is interesting to note. Low recurrence rate in limited follow-up period could be due to early detection and standard management.
Asunto(s)
Adolescente , Adulto , Animales , Niño , Preescolar , Conjuntiva/parasitología , Enfermedades de la Conjuntiva/epidemiología , Diagnóstico Diferencial , Infecciones Parasitarias del Ojo/epidemiología , Femenino , Estudios de Seguimiento , Hospitales Comunitarios , Humanos , Incidencia , India/epidemiología , Lactante , Recién Nacido , Aparato Lagrimal/parasitología , Enfermedades del Aparato Lagrimal/epidemiología , Masculino , Estudios Retrospectivos , Rinosporidiosis/epidemiología , Rhinosporidium/aislamiento & purificaciónRESUMEN
Although rhinsporidiosis caused by Rhinosporidium seeberi is known to mankind since hundred years, many aspects of this enigmatic disease have remained mysterious till date. Parotid duct as a site of involvement has rarely been reported. Our case interestingly presented with a cystic mass of left parotid duct accompanied by an ulcer and mucopurulent discharge was finally confirmed to be a case of rhinosporidiosis by histopathological examination.
Asunto(s)
Anciano , Animales , Humanos , Masculino , Enfermedades de las Parótidas/diagnóstico , Rinosporidiosis/diagnóstico , Rhinosporidium/aislamiento & purificación , Esporas Protozoarias/aislamiento & purificaciónRESUMEN
A young Hindu male presented with painful swelling of left lower thigh for 6 months.The provisional diagnosis both clinically and radiologically was osteosarcoma. FNAC and biopsy proved the lesion to be a case of rhinosporidiosis. The present case is reported due to rare incidence of skeletal rhinosporidiosis.
Asunto(s)
Adulto , Animales , Biopsia con Aguja Fina , Enfermedades Óseas/diagnóstico , Citodiagnóstico , Fémur , Humanos , Masculino , Rinosporidiosis/diagnóstico , Rhinosporidium/aislamiento & purificación , Esporas/aislamiento & purificaciónRESUMEN
Se hace una revisión de la rinosporidiosis. Además, se informa el primer caso en Costa Rica, diagnosticado en un paciente de 19 años de edad, vecino del cantón de Turrialba, a quien se le encontró un pólipo nasal con Rhinosporidium seeberi. Seis meses después del diagnóstico inicial, el paciente presentó recidiva