A Case of Grisel Syndrome Showing No Underlying Laxity of the Atlanto-axial Joint
Annals of Rehabilitation Medicine
;
: 511-515, 2017.
Article
in English
| WPRIM
| ID: wpr-49259
ABSTRACT
Grisel syndrome is a rare, non-traumatic atlanto-axial subluxation associated with an inflammatory or infectious process in the upper neck. According to the two-hit hypothesis, which is widely accepted for the pathogenesis of Grisel syndrome, preexisting ligamentous laxity of the atlanto-axial joint is regarded as the first hit. An inflammatory or infectious process of the atlanto-axial joint acts as the second hit, resulting in non-traumatic atlanto-axial subluxation. We report on a 6-year-old girl with atlanto-axial subluxation following retropharyngeal and cervical lymphadenitis. She was diagnosed with Grisel syndrome, for which an initial computed tomography did not show any preexisting ligamentous laxity of the atlanto-axial joint. A literature review found only 4 case reports on Grisel syndrome with an initially normal atlanto-axial joint. The present case offers some evidence that a single hit, such as inflammatory changes in the atlanto-axial joint, might cause Grisel syndrome, even without underlying ligamentous laxity.
Full text:
Available
Index:
WPRIM (Western Pacific)
Main subject:
Atlanto-Axial Joint
/
Torticollis
/
Joint Instability
/
Ligaments
/
Lymphadenitis
/
Neck
Limits:
Child
/
Female
/
Humans
Language:
English
Journal:
Annals of Rehabilitation Medicine
Year:
2017
Type:
Article
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