Your browser doesn't support javascript.
loading
Show: 20 | 50 | 100
Results 1 - 1 de 1
Filter
Add more filters










Database
Language
Publication year range
1.
Fam Cancer ; 19(3): 241-246, 2020 07.
Article in English | MEDLINE | ID: mdl-32052252

ABSTRACT

Despite the acceptance of NextGen sequencing as a diagnostic modality suitable for probands and carriers of Mendelian diseases, its efficiency in identifying causal mutations is limited by both technical aspects of variant call algorithms and by imperfect, consensus-based criteria for assessing the pathogenicity of the findings. Here we describe the medical history of the family with a child born with Fanconi anemia. In this case, typical diagnostic routines were complicated by unusual combination of mutations. PALB2 variant NM_024675.3:c.172_175delTTGT (p.Gln60Argfs) in maternal sample, previously classified as a definitely pathogenic frameshift mutation, was in compound heterozygous state with PALB2 NM_024675.3:c.3114-16_3114-11del (p.Asn1039Glyfs*7), which led to validated PALB2 exon 11 skipping event in paternal locus. Findings enabled the development of the PGТ and successful selection of two mutation-free embryos. We show that even in absence of definitive exome findings, clinician-guided research inquiries into the structure and function of the suspected loci allow definitive diagnosis. Described case provides an example of a crucial input of an investigational workflow in genetic prognosis and successful PGT.


Subject(s)
Fanconi Anemia Complementation Group N Protein/genetics , Fanconi Anemia/genetics , Frameshift Mutation , Introns/genetics , Adult , Child, Preschool , Exons , Fanconi Anemia/diagnosis , Fanconi Anemia/prevention & control , Fatal Outcome , Female , Fertilization in Vitro/methods , Genetic Testing/methods , High-Throughput Nucleotide Sequencing , Humans , Infant , Male , Parents , Preimplantation Diagnosis/methods , RNA, Messenger/analysis , RNA, Messenger/genetics , Exome Sequencing/methods
SELECTION OF CITATIONS
SEARCH DETAIL
...