Atypical Cogan's syndrome associated with coronary disease / 中华医学杂志(英文版)
Chinese Medical Journal
; (24): 3192-3194, 2011.
Article
in En
| WPRIM
| ID: wpr-319173
Responsible library:
WPRO
ABSTRACT
Cogan’s syndrome (CS) is a rare inflammatory disorder characterized by interstitial keratitis and vestibuloauditory abnormalities often associated with various systemic manifestations. Involvement of cardiovascular system resembling systemic vasculitis may lead to severe complications and death. The present report describes a case of a female patient with atypical Cogan's syndrome presented with systemic manifestations and severe coronary and femoral artery stenosis. Despite the clinical improvement after glucocorticoids and cyclophosphamide, the patient required double aortocoronal bypass grafting one year letter. During three years follow-up, she was in stable condition, without stenocardial symptoms and claudication and her inflammatory parameters remain normal. This case highlights the rare involvement of coronary arteries without associated large-vessel vasculitis of the aortic arch in CS.
Full text:
1
Database:
WPRIM
Main subject:
Coronary Disease
/
Cogan Syndrome
Limits:
Adult
/
Female
/
Humans
Language:
En
Journal:
Chinese Medical Journal
Year:
2011
Document type:
Article